Comprehensive mapping of genetic variation at Epromoters reveals pleiotropic association with multiple disease traits DOI Creative Commons
Jing Wan,

Antoinette van Ouwerkerk,

Jean-Christophe Mouren

и другие.

Nucleic Acids Research, Год журнала: 2024, Номер unknown

Опубликована: Дек. 19, 2024

Abstract There is growing evidence that a wide range of human diseases and physiological traits are influenced by genetic variation cis-regulatory elements. We others have shown subset promoter elements, termed Epromoters, also function as enhancer regulators distal genes. This opens paradigm in the study regulatory variants, single nucleotide polymorphisms (SNPs) within Epromoters might influence expression several (distal) genes at same time, which could disentangle identification disease-associated Here, we built comprehensive resource using newly generated publicly available high-throughput reporter assays. showed display intrinsic epigenetic features distinguish them from typical promoters. By integrating Genome-Wide Association Studies (GWAS), Quantitative Trait Loci (eQTLs) 3D chromatin interactions, found variants concurrently associated with more disease traits, compared To dissect impact Epromoter evaluated their on activity analyzing allelic-specific assays provided reliable examples pleiotropic Epromoters. In summary, our represents supporting role

Язык: Английский

Genetic architecture of human brain evolution DOI Creative Commons

Tyler Fair,

Alex A. Pollen

Current Opinion in Neurobiology, Год журнала: 2023, Номер 80, С. 102710 - 102710

Опубликована: Март 30, 2023

Comparative studies of hominids have long sought to identify mutational events that shaped the evolution human nervous system. However, functional genetic differences are outnumbered by millions nearly neutral mutations, and developmental mechanisms underlying system specializations difficult model incompletely understood. Candidate-gene attempted map select human-specific neurodevelopmental functions, but it remains unclear how contextualize relative effects genes investigated independently. Considering these limitations, we discuss scalable approaches for probing contributions differences. We propose a systems-level view will enable more quantitative integrative understanding genetic, molecular cellular underpinnings evolution.

Язык: Английский

Процитировано

13

Massively parallel assessment of gene regulatory activity at human cortical structure associated variants DOI Creative Commons
Nana Matoba, Jessica C. McAfee,

Oleh Krupa

и другие.

bioRxiv (Cold Spring Harbor Laboratory), Год журнала: 2025, Номер unknown

Опубликована: Фев. 8, 2025

Abstract Genetic association studies have identified hundreds of largely non-coding loci associated with inter-individual differences in the structure human cortex, though specific genetic variants that impact regulatory activity are unknown. We implemented a Massively Parallel Reporter Assay (MPRA) to measure 9,092 cortical DNA neural progenitor cells during Wnt stimulation and at baseline. 918 potential from 150 (76% studied), which >50% showed allelic effects. modified subset functioned as condition-dependent enhancers. Regulatory MPRA was induced by Alu elements were hypothesized contribute expansion. The regionally disrupt motifs is likely mediated through levels transcription factor expression development, further clarifying molecular mechanisms altering structure.

Язык: Английский

Процитировано

0

Comparative genomics illuminates karyotype and sex chromosome evolution of sharks DOI Creative Commons
Jiahong Wu, Fujiang Liu, Jie Jiao

и другие.

Cell Genomics, Год журнала: 2024, Номер 4(8), С. 100607 - 100607

Опубликована: Июль 11, 2024

Chondrichthyes is an important lineage to reconstruct the evolutionary history of vertebrates. Here, we analyzed genome synteny for six chondrichthyan chromosome-level genomes. Our comparative analysis reveals a slow rate chromosomal changes, with infrequent but independent fusions observed in sharks, skates, and chimaeras. The common ancestor had proto-vertebrate-like karyotype, including presence 18 microchromosome pairs. X chromosome conversed shared by all suggesting likely origin sex at least 181 million years ago. We characterized Y chromosomes two sharks that are highly differentiated from except small young stratum pseudoautosomal region. found shark lack global dosage compensation dosage-sensitive genes locally compensated. study on evolution enhances our understanding vertebrate evolution.

Язык: Английский

Процитировано

3

Transcription of Endogenous Retroviruses: Broad and Precise Mechanisms of Control DOI Creative Commons

Abigail Jarosz,

Julia V. Halo

Viruses, Год журнала: 2024, Номер 16(8), С. 1312 - 1312

Опубликована: Авг. 17, 2024

Endogenous retroviruses (ERVs) are the remnants of retroviral germline infections and highly abundant in genomes vertebrates. At one time considered to be nothing more than inert ‘junk’ within genomes, ERVs have been tolerated host over vast timescales, their study continues reveal complex co-evolutionary histories respective species. For example, multiple instances characterized having ‘borrowed’ for normal physiology, from single copies ones involved various regulatory networks such as innate immunity during early development. Within cell, accessibility is normally tightly controlled by epigenetic mechanisms DNA methylation or histone modifications. However, these silencing reversible, alterations chromatin landscape can thus lead aberrant expression, observed abnormal cellular environments tumors. In this review, we focus on ERV transcriptional control draw parallels distinctions concerning loss regulation disease, well precise

Язык: Английский

Процитировано

3

Novelty versus innovation of gene regulatory elements in human evolution and disease DOI Creative Commons

Anushka Katikaneni,

Craig B. Lowe

Current Opinion in Genetics & Development, Год журнала: 2024, Номер 90, С. 102279 - 102279

Опубликована: Ноя. 26, 2024

Язык: Английский

Процитировано

2

Transforming our understanding of species-specific gene regulation DOI Creative Commons
Megan Y. Dennis

Cell Genomics, Год журнала: 2024, Номер 4(4), С. 100540 - 100540

Опубликована: Апрель 1, 2024

Mechanisms underlying phenotypic divergence across species remain unresolved. In this issue of Cell Genomics, Hansen, Fong, et al.

Язык: Английский

Процитировано

0

Uncovering methylation-dependent genetic effects on regulatory element function in diverse genomes DOI Open Access
Rachel M. Petersen, Christopher M. Vockley, Amanda J. Lea

и другие.

bioRxiv (Cold Spring Harbor Laboratory), Год журнала: 2024, Номер unknown

Опубликована: Авг. 24, 2024

ABSTRACT A major goal in evolutionary biology and biomedicine is to understand the complex interactions between genetic variants, epigenome, gene expression. However, causal relationships these factors remain poorly understood. mSTARR-seq, a methylation-sensitive massively parallel reporter assay, capable of identifying methylation-dependent regulatory activity at many thousands genomic regions simultaneously, allows for testing DNA methylation expression on region-by-region basis. Here, we developed multiplexed mSTARR-seq protocol assay naturally occurring human variation from 25 individuals sampled 10 localities Europe Africa. We identified 6,957 elements either unmethylated or methylated state, this set was enriched enhancer promoter annotations, as expected. The 58% modulated by methylation, which generally associated with decreased RNA Within our elements, used allele-specific analyses identify 8,020 sites effects regulation; further, found that 42.3% varied states. Sites exhibiting were GWAS EWAS implicating them disease. Compared datasets single European individual, uncovers dramatically more effects, highlighting importance including diverse assays aim processes.

Язык: Английский

Процитировано

0

Comprehensive mapping of genetic variation at Epromoters reveals pleiotropic association with multiple disease traits DOI Creative Commons
Jing Wan,

Antoinette van Ouwerkerk,

Jean-Christophe Mouren

и другие.

Nucleic Acids Research, Год журнала: 2024, Номер unknown

Опубликована: Дек. 19, 2024

Abstract There is growing evidence that a wide range of human diseases and physiological traits are influenced by genetic variation cis-regulatory elements. We others have shown subset promoter elements, termed Epromoters, also function as enhancer regulators distal genes. This opens paradigm in the study regulatory variants, single nucleotide polymorphisms (SNPs) within Epromoters might influence expression several (distal) genes at same time, which could disentangle identification disease-associated Here, we built comprehensive resource using newly generated publicly available high-throughput reporter assays. showed display intrinsic epigenetic features distinguish them from typical promoters. By integrating Genome-Wide Association Studies (GWAS), Quantitative Trait Loci (eQTLs) 3D chromatin interactions, found variants concurrently associated with more disease traits, compared To dissect impact Epromoter evaluated their on activity analyzing allelic-specific assays provided reliable examples pleiotropic Epromoters. In summary, our represents supporting role

Язык: Английский

Процитировано

0