Exploring SVA Insertion Polymorphisms in Shaping Differential Gene Expression in the Central Nervous System DOI Open Access
Lauren S. Hughes, Alexander Fröhlich, Abigail L. Pfaff

и другие.

Опубликована: Дек. 26, 2023

Transposable elements (TEs) are repetitive which make up around 45% of the human genome. A class TEs known as SINE-VNTR-Alu (SVA) demonstrate capacity to mobilise throughout genome, resulting in SVA polymorphisms for presence or absence within population. Although studies have previously highlighted involvement neurodegenerative diseases, such Parkinson’s disease and amyotrophic lateral sclerosis (ALS), however exact mechanism has yet be identified. In this study we used whole genome sequencing RNA data ALS patients healthy controls from New York Genome Center Consortium, elucidate influence reference on gene expression genome-wide central nervous system (CNS) tissues. To investigate this, applied matrix quantitative trait loci analysis demonstrated that insertion can significantly modulate numerous genes, preferentially trans position, a tissue-specific manner. We also highlight SVAs regulate mitochondrial genes well HLA MAPT loci, associated disease. conclusion, continues bring light effects polymorphic regulation further highlights importance pathology.

Язык: Английский

Regulatory SVA retrotransposons and classical HLA genotyped-transcripts associated with Parkinson’s disease DOI Creative Commons
Jerzy K. Kulski, Shingo Suzuki, Takashi Shiina

и другие.

Frontiers in Immunology, Год журнала: 2024, Номер 15

Опубликована: Март 25, 2024

Introduction Parkinson’s disease (PD) is a neurodegenerative and polygenic disorder characterised by the progressive loss of neural dopamine onset movement disorders. We previously described eight SINE-VNTR-Alu (SVA) retrotransposon-insertion-polymorphisms (RIPs) located expressed within Human Leucocyte Antigen (HLA) genomic region chromosome 6 that modulate differential co-expression 71 different genes including HLA classical class I II in Progression Markers Initiative (PPMI) cohort. Aims methods In present study, we (1) reanalysed PPMI transcriptomic sequencing data obtained from whole blood 1521 individuals (867 cases 654 controls) to infer genotypes transcripts as well DRA DRB3/4/5 haplotypes, (2) examined statistical differences between three PD subgroups (cases) healthy controls (HC) for SVA transcribed inferred haplotypes. Results Significant 57 alleles (21 36 alleles) up three-field resolution four were detected at p<0.05 Fisher’s exact test one or other (750 with PD, prodromes, 60 who had scans without evidence deficits [SWEDD]), when compared against group HCs cohort not corrected Bonferroni multiple comparisons. Fourteen 20 significant unique PD-HC comparison, whereas 31 overlapped two more subgroup Only HLA-DRA*01:01:01 - DQA1*03:01:01 protective (PD v HC), -DQA1*03:03:01 risk (HC Prodrome) allele Prodrome), -DRA*01:01:02 DRB4*01:03:02 (SWEDD NR_SVA_381 genotype HC) 5% homozygous insertion frequency near HLA-DPA1 , ( Pc<0.1 ) after corrections. The homologous significantly decreased transcription levels HLA-DPB1 its presence factor Pc=0.012 PD. most frequent haplotype was NR_SVA_381/DPA1*02/DPB1*01 (3.7%). Although C*07/B*07/DRB5*01/DRB1*15/DQB1*06 5-loci phased-haplotype (n, 76) cohort, only six them (8%). Conclusions These suggest gene circulating white cells are coordinated differentially regulation immune responses long-term progression mechanisms which have yet be elucidated.

Язык: Английский

Процитировано

7

The Transcription of Transposable Elements Differentially Regulated by SVAs in the Major Histocompatibility Complex Class I Region of a Parkinson’s Progression Markers Initiative Cohort DOI Creative Commons
Jerzy K. Kulski, Abigail L. Pfaff,

Sulev Kõks

и другие.

Journal of Molecular Pathology, Год журнала: 2025, Номер 6(1), С. 1 - 1

Опубликована: Янв. 6, 2025

Background/Objectives: The highly polymorphic Major Histocompatibility Complex (MHC) genomic region, located on the short arm of chromosome 6, is implicated genetically in Parkinson’s disease (PD), a progressive neurodegenerative disorder with motor and non-motor symptoms. Previously, we reported significant associations between SINE-VNTR-Alu (SVA) expression quantitative trait loci (eQTLs) Human Leucocyte Antigen (HLA) class I genotypes PD. In this study, aimed to evaluate SVA their regulatory effects transposable element (TE) transcription MHC region. Methods: Transcriptome data from peripheral blood cells 1530 individuals Progression Markers Initiative (PPMI) cohort were reanalyzed for TE gene using publicly available bioinformatics tools, including Salmon Matrix-eQTL. Results: Four structurally SVAs regulated 18 distinct clusters 235 loci, comprising LINEs (33%), SINEs (19%), LTRs (35%), ancient transposon DNA elements (12%) near HLA genes. transcribed TEs predominantly short, an average length 445 nucleotides. these varied significantly terms types, numbers, transcriptional activation or repression. SVA-regulated RNAs appear function as enhancer-like elements, differentially influencing genes, non-HLA noncoding RNAs. Conclusions: These findings highlight roles associated complex networks governing coding potential implications immune susceptibility.

Язык: Английский

Процитировано

0

scTCR-seq and HTS reveal a special novel TRBD2-TRBJ1 rearrangement in mammalian TRB CDR3 repertoire DOI Creative Commons
Yingjie Wu, Fengli Wu, Jun Li

и другие.

BMC Genomics, Год журнала: 2025, Номер 26(1)

Опубликована: Апрель 4, 2025

Mammalian T cell receptor (TCR) beta-chain (TRB) V-D-J rearrangement mainly follows the "12/23 rule", and "D-J preceding V-(D-J) rearrangement". Owing to physical position of D-J-C cluster in TRB locus, TRBD2 (D2) gene cannot directly perform inversional or deletional/loop-out with TRBJ1 (J1) gene. Our previous studies revealed a single reverse TRBV30 (TRBV31 mice) mammalian which can cause indirect D2 J1 gene; however, mechanism proportion involved germline are unknown. We obtained CDR3 repertoires thymus peripheral tissues from humans mice by HTS scTCR-seq found that 14% rearrangements is D2-J1 (D2-J2 account for approximately 86%). The V30 preferentially performs (V30-D2), leading V30-D2-J1 humans, D1 (V30-D1), allowing forward V genes (Vx) Vx-D2-J1 rearrangement. further were present more than 24% 15% rhesus monkeys bats, respectively. Moreover, bovine containing D1J1C1, D3J3C3, D2J2C2 clusters, 11% D3-J1 22% D2-J3 found. This study provides new perspective feasible solution research on significance special recombination pattern locus repertoire formed

Язык: Английский

Процитировано

0

Analysis of HLA-G 14 bp Insertion/Deletion Polymorphism and HLA-G, ILT2 and ILT4 Expression in Head and Neck Squamous Cell Carcinoma Patients DOI Creative Commons
Vladimı́ra Ďurmanová, Miroslav Tedla,

Dusan Rada

и другие.

Diseases, Год журнала: 2024, Номер 12(2), С. 34 - 34

Опубликована: Фев. 8, 2024

HLA-G is the checkpoint molecule involved in suppression of immune response. Increased expression and its ILTs receptors have been correlated with tumor progression various cancer types. In head neck squamous cell carcinoma (HNSCC) tumors, effect HLA-G, ILT2 ILT4 on development has to be explained. The 34 HNSCC patients 98 controls were genotyped for 14 bp ins/del polymorphism. lesions, mRNA was analysed using real-time PCR. association between clinical variables (age at onset, TNM staging system p16 positivity) also evaluated. No genetic risk detected (p > 0.05). However, non-metastatic group, a significantly higher noted tumors T4 stage compared those T1 T2 stages = 0.0289). increased vs. metastatic 0.0269). Furthermore, T1+T2 T3 0.0495). Our results suggest that creates an immunological microenvironment development.

Язык: Английский

Процитировано

2

Exploring SVA Insertion Polymorphisms in Shaping Differential Gene Expressions in the Central Nervous System DOI Creative Commons
Lauren S. Hughes, Alexander Fröhlich, Abigail L. Pfaff

и другие.

Biomolecules, Год журнала: 2024, Номер 14(3), С. 358 - 358

Опубликована: Март 17, 2024

Transposable elements (TEs) are repetitive which make up around 45% of the human genome. A class TEs, known as SINE-VNTR-Alu (SVA), demonstrate capacity to mobilise throughout genome, resulting in SVA polymorphisms for their presence or absence within population. Although studies have previously highlighted involvement TEs neurodegenerative diseases, such Parkinson’s disease and amyotrophic lateral sclerosis (ALS), exact mechanism has yet be identified. In this study, we used whole-genome sequencing RNA data ALS patients healthy controls from New York Genome Centre Consortium elucidate influence reference on gene expressions genome-wide central nervous system (CNS) tissues. To investigate this, applied a matrix expression quantitative trait loci analysis that insertion can significantly modulate numerous genes, preferentially trans position tissue-specific manner. We also highlight SVAs regulate mitochondrial genes well HLA MAPT loci, associated diseases. conclusion, study continues bring light effects polymorphic regulation further highlights importance pathology.

Язык: Английский

Процитировано

2

SVA Regulation of Transposable Element Clustered Transcription within the Major Histocompatibility Complex Genomic Class II Region of the Parkinson’s Progression Markers Initiative DOI Open Access
Jerzy K. Kulski, Abigail L. Pfaff,

Sulev Kõks

и другие.

Genes, Год журнала: 2024, Номер 15(9), С. 1185 - 1185

Опубликована: Сен. 9, 2024

SINE-VNTR-Alu (SVA) retrotransposons can regulate expression quantitative trait loci (eQTL) of coding and noncoding genes including transposable elements (TEs) distributed throughout the human genome. Previously, we reported that expressed SVAs leucocyte antigen (HLA) class II genotypes on chromosome 6 were associated significantly with Parkinson’s disease (PD). Here, our aim was to follow-up previous study evaluate SVA associations their regulatory effects transcription TEs within HLA genomic region. We reanalyzed transcriptome data peripheral blood cells from Progression Markers Initiative (PPMI) for 1530 subjects TE gene RNAs publicly available computing packages. Four structurally polymorphic 20 distinct clusters 235 represented by LINES (37%), SINES (28%), LTR/ERVs (23%), ancient transposon DNA (12%) are located in close proximity genes. The transcribed mostly short length, an average size 389 nucleotides. numbers, types profiles positive negative regulation varied markedly between four SVAs. appear be enhancer-like coordinated differentially Future work mechanisms underlying potential impact is essential elucidating roles normal cellular processes pathogenesis.

Язык: Английский

Процитировано

2

Exploring the HLA complex in autoimmunity: From the risk haplotypes to the modulation of expression DOI Creative Commons
Silvia Sartoris, Giovanna Del Pozzo

Clinical Immunology, Год журнала: 2024, Номер 265, С. 110266 - 110266

Опубликована: Июнь 7, 2024

The genes mapping at the HLA region show high density, strong linkage disequilibrium and polymorphism, which affect association of class I II with autoimmunity. We focused on haplotypes, genomic structures consisting an array specific alleles showing some degrees genetic different autoimmune disorders. GWASs in many pathologies have identified variants either coding loci or flanking regulatory regions, both that are frequently associated increased risk may influence gene expression. discuss relevance expression because level surface heterodimers determines number complexes presenting self-antigen and, thus, strength pathogenic autoreactive T cells immune response.

Язык: Английский

Процитировано

1

Human Leukocyte Antigen and microRNAs as Key Orchestrators of Mild Cognitive Impairment and Alzheimer’s Disease: A Systematic Review DOI Open Access
Cristina-Sorina Cătană, Monica Mihaela Marta, Mădălina Văleanu

и другие.

International Journal of Molecular Sciences, Год журнала: 2024, Номер 25(15), С. 8544 - 8544

Опубликована: Авг. 5, 2024

The expression of inflamma-miRs and human leukocyte antigen (HLA) haplotypes could indicate mild cognitive impairment (MCI) Alzheimer’s disease (AD). We used international databases to conduct a systematic review studies on HLA variants meta-analysis research microRNAs (miRNAs). aimed analyze the discriminative value miRNAs in MCI, AD controls evaluate protective or causative effect decline, establish role as biomarkers for early detection AD, find possible link between HLA. Statistical analysis was conducted using Comprehensive Meta-analysis software, version 2.2.050 (Biostat Inc., Englewood, NJ, USA). sizes were estimated by logarithm base 2 fold change. revealed that some variants, such HLA-B*4402, HLA-A*33:01, HLA-DPB1, HLA-DR15, HLA-DQB1*03:03, HLA-DQB1*06:01, HLA-DQB1*03:01, SNPs HLA-DRB1/DQB1, HLA-DQA1, predisposed decline before occurrence while HLA-A1*01, HLA-DRB1∗13:02, HLA-DRB1*04:04, HLA-DRB1*04:01 demonstrated role. identified let-7 miR-15/16 AD. association these two miRNA families predispose be screening prevention MCI.

Язык: Английский

Процитировано

1

Exploring SVA Insertion Polymorphisms in Shaping Differential Gene Expression in the Central Nervous System DOI Open Access
Lauren S. Hughes, Alexander Fröhlich, Abigail L. Pfaff

и другие.

Опубликована: Дек. 26, 2023

Transposable elements (TEs) are repetitive which make up around 45% of the human genome. A class TEs known as SINE-VNTR-Alu (SVA) demonstrate capacity to mobilise throughout genome, resulting in SVA polymorphisms for presence or absence within population. Although studies have previously highlighted involvement neurodegenerative diseases, such Parkinson’s disease and amyotrophic lateral sclerosis (ALS), however exact mechanism has yet be identified. In this study we used whole genome sequencing RNA data ALS patients healthy controls from New York Genome Center Consortium, elucidate influence reference on gene expression genome-wide central nervous system (CNS) tissues. To investigate this, applied matrix quantitative trait loci analysis demonstrated that insertion can significantly modulate numerous genes, preferentially trans position, a tissue-specific manner. We also highlight SVAs regulate mitochondrial genes well HLA MAPT loci, associated disease. conclusion, continues bring light effects polymorphic regulation further highlights importance pathology.

Язык: Английский

Процитировано

1