Motile Cilia in Female and Male Reproductive Tracts and Fertility DOI Creative Commons
Dorota Włoga, Ewa Joachimiak, Anna Osinka

и другие.

Cells, Год журнала: 2024, Номер 13(23), С. 1974 - 1974

Опубликована: Ноя. 28, 2024

Motile cilia are evolutionarily conserved organelles. In humans, multiciliated cells (MCCs), assembling several hundred motile on their apical surface, components of the monolayer epithelia lining lower and upper airways, brain ventricles, parts reproductive tracts, fallopian tube uterus in females, efferent ductules males. The coordinated beating generates a force that enables shift tubular fluid, particles, or along surface ciliated epithelia. Uncoordinated altered motion immotility may result subfertility even infertility. Here, we summarize current knowledge regarding localization function MCCs human discuss how beating-generated fluid flow directly indirectly contribute to processes these organs, lack improper functioning influence fertility.

Язык: Английский

Impact of Metal Ions on Cellular Functions: A Focus on Mesenchymal Stem/Stromal Cell Differentiation DOI Open Access
Kirsten Peters,

Susanne Staehlke,

Henrike Rebl

и другие.

International Journal of Molecular Sciences, Год журнала: 2024, Номер 25(18), С. 10127 - 10127

Опубликована: Сен. 20, 2024

Metals play a crucial role in the human body, especially as ions metalloproteins. Essential metals, such calcium, iron, and zinc are for various physiological functions, but their interactions within biological networks complex not fully understood. Mesenchymal stem/stromal cells (MSCs) essential tissue regeneration due to ability differentiate into cell types. This review article addresses effects of unphysiological, directly toxic, metal ion concentrations, particularly concerning MSCs. Overloading or unbalancing concentrations can significantly impair function differentiation capacity In addition, excessive unbalanced lead oxidative stress, which affect viability inflammation. Data on MSC limited often contradictory. Future research should, therefore, aim clarify mechanisms by differentiation, focusing aspects interactions, exposure duration, other environmental conditions. Understanding these could ultimately improve design biomaterials implants promote MSC-mediated regeneration. It also development innovative therapeutic strategies regenerative medicine.

Язык: Английский

Процитировано

11

A network of interacting ciliary tip proteins with opposing activities imparts slow and processive microtubule growth DOI Creative Commons
Harriet A. J. Saunders, Cyntha M. van den Berg,

Robin Hoogebeen

и другие.

Nature Structural & Molecular Biology, Год журнала: 2025, Номер unknown

Опубликована: Янв. 24, 2025

Abstract Cilia are motile or sensory organelles present on many eukaryotic cells. Their formation and function rely axonemal microtubules, which exhibit very slow dynamics, but the underlying mechanisms largely unexplored. Here we reconstituted in vitro individual collective activities of ciliary tip module proteins CEP104, CSPP1, TOGARAM1, ARMC9 CCDC66, interact with each other microtubules and, when mutated humans, cause ciliopathies such as Joubert syndrome. We show that a protein tubulin-binding TOG domain, its luminal partner CSPP1 inhibit microtubule growth shortening. Another TOG-domain protein, overcomes inhibition imposed by CEP104 CSPP1. CCDC66 do not affect dynamics act scaffolds for their partners. Cryo-electron tomography demonstrated that, together, members form plus-end-specific cork-like structures reduce protofilament flaring. The combined effect these is processive elongation, recapitulates

Язык: Английский

Процитировано

2

Axonemal microtubule dynamics in the assembly and disassembly of cilia DOI Creative Commons
Yi Zhang, Mu He, Junmin Pan

и другие.

Biochemical Society Transactions, Год журнала: 2025, Номер 53(1)

Опубликована: Янв. 31, 2025

Cilia and eukaryotic flagella (exchangeable terms) function in cell motility signaling, which are pivotal for development physiology. dysfunction can lead to ciliopathies. usually assembled quiescent and/or differentiated cells undergo disassembly when enter cycle or response environmental stresses. contain a microtubule-based structure termed axoneme that comprises nine outer doublet microtubules with without pair of central microtubules, is ensheathed by the ciliary membrane. Regulation axonemal microtubule dynamics tightly associated assembly disassembly. In this short review, we discuss recent findings on regulation microtubule-binding proteins modulating kinesins during

Язык: Английский

Процитировано

0

Centrosome biogenesis and maintenance in homeostasis and disease DOI

Camila Fernandes-Mariano,

Joana N. Bugalhão, Diana Santos

и другие.

Current Opinion in Cell Biology, Год журнала: 2025, Номер 94, С. 102485 - 102485

Опубликована: Фев. 24, 2025

Язык: Английский

Процитировано

0

Phosphorylation at the Helm: Kinase‐Mediated Regulation of Primary Cilia Assembly and Disassembly DOI Creative Commons
Andrea Lacigová, Lukáš Čajánek

Cytoskeleton, Год журнала: 2025, Номер unknown

Опубликована: Март 10, 2025

The primary cilium serves as an antenna of most vertebrate cells and is important for conveying cues from several signaling pathways into appropriate cellular responses during development homeostasis. Cilia assembly disassembly processes are thought to be strictly controlled; however, the precise nature molecular events underlying this control still awaits full resolution. Through their enzymatic activity, kinases function flexible yet highly controllable regulators a vast variety processes. Their activity ranges cell cycle regulation motility, signal transduction, metabolism. This review focuses on emerging role in cilia biology. We underscore functions formation, maintenance, resorption while examining available models respective mechanisms actions.

Язык: Английский

Процитировано

0

Microtubule-Associated Proteins (MAPs) Are Multifunctional Cytoskeletal Proteins in the Testis That Regulate Spermatogenesis DOI
Lingling Wang,

Tiao Bu,

Xiaolong Wu

и другие.

Advances in experimental medicine and biology, Год журнала: 2025, Номер unknown, С. 411 - 431

Опубликована: Янв. 1, 2025

Язык: Английский

Процитировано

0

A network of interacting ciliary tip proteins with opposing activities imparts slow and processive microtubule growth DOI Creative Commons
Harriet A. J. Saunders, Cyntha M. van den Berg,

Robin Hoogebeen

и другие.

bioRxiv (Cold Spring Harbor Laboratory), Год журнала: 2024, Номер unknown

Опубликована: Март 26, 2024

Abstract Cilia are essential motile or sensory organelles found on many eukaryotic cells. Their formation and function rely axonemal microtubules, which exhibit very slow dynamics, however the underlying biochemical mechanisms largely unexplored. Here, we reconstituted in vitro individual collective activities of ciliary tip module proteins, CEP104, CSPP1, TOGARAM1, ARMC9 CCDC66, interact with each other and, when mutated, cause ciliopathies such as Joubert syndrome. a protein containing tubulin-binding TOG domain, is an inhibitor microtubule growth shortening that interacts EBs surface luminal microtubule-pausing factor CSPP1. Another TOG-domain protein, overcomes inhibition imposed by CEP104 CCDC66 do not affect dynamics directly but act scaffolds for their partners. Cryo-electron tomography showed together, members form plus-end-specific cork-like structures reduce protofilament flaring. The combined effect these proteins processive elongation, recapitulates

Язык: Английский

Процитировано

2

Variants in the AGBL5 gene are responsible for autosomal recessive Retinitis pigmentosa with hearing loss DOI Creative Commons
Marianthi Karali, Gema García‐García, Karolina Kamińska

и другие.

European Journal of Human Genetics, Год журнала: 2024, Номер unknown

Опубликована: Дек. 13, 2024

Abstract The AGBL5 gene encodes for the Cytoplasmic Carboxypeptidase 5 (CCP5), an α-tubulin deglutamylase that cleaves γ-carboxyl-linked branching point of glutamylated tubulin. To date, pathogenic variants in have been associated only with isolated retinitis pigmentosa (RP). Hearing loss has not reported -caused retinal disease. In this study, we performed exome sequencing probands eight unrelated families from Italy, Spain, Palestine, Switzerland, and Greece. All subjects had a clinical diagnosis (suspected) Usher syndrome type II concurrent presence RP post-verbal sensorineural hearing (SNHL) ranged mild to moderate.We identified biallelic sequence all analysed subjects. Four were novel. co-segregated auditory phenotypes additional affected family members. We did detect any causative known deafness or genes could explain patients’ loss. therefore conclude SNHL is feature syndromic presentation retinopathy. This study provides first evidence mutations can cause forms loss, probably due dysfunction sensory cilia retina inner ear.

Язык: Английский

Процитировано

2

Ccdc66 regulates primary cilium stability, disassembly and signaling important for epithelial organization DOI Creative Commons
Jovana Deretic, Seyma Cengiz-Emek,

Ece Seyrek

и другие.

bioRxiv (Cold Spring Harbor Laboratory), Год журнала: 2024, Номер unknown

Опубликована: Июнь 17, 2024

Abstract The primary cilium is a conserved, microtubule-based organelle that transduces signaling pathways essential for development and homeostasis. It dynamic structure assembles disassembles in response to intrinsic extrinsic stimuli while maintaining remarkable stability tightly controlled length. Although assembly well-understood, less known about the molecular players governing their stability, length disassembly. Here, we elucidated function of Ccdc66, microtubule-associated protein linked ciliopathies, maintenance disassembly mouse epithelial cells. We found Ccdc66 depletion disrupts disassembly, but does not affect these Live imaging processes revealed cilia Ccdc66-depleted cells frequently fluctuate exhibit increased ectocytosis from tip. Phenotypic rescue experiments vitro microtubule stabilization assays showed mediates functions via regulating microtubules. Temporal proximity mapping CCDC66 identified potential new regulators involved Additionally, compromised Hedgehog Wnt pathway activation disrupted cell organization polarity two-dimensional three-dimensional cultures. Collectively, our results define as microtubule-stabilizing factor regulates providing insights into mechanisms homeostasis pathologies associated with Ccdc66.

Язык: Английский

Процитировано

1

Motile Cilia in Female and Male Reproductive Tracts and Fertility DOI Creative Commons
Dorota Włoga, Ewa Joachimiak, Anna Osinka

и другие.

Cells, Год журнала: 2024, Номер 13(23), С. 1974 - 1974

Опубликована: Ноя. 28, 2024

Motile cilia are evolutionarily conserved organelles. In humans, multiciliated cells (MCCs), assembling several hundred motile on their apical surface, components of the monolayer epithelia lining lower and upper airways, brain ventricles, parts reproductive tracts, fallopian tube uterus in females, efferent ductules males. The coordinated beating generates a force that enables shift tubular fluid, particles, or along surface ciliated epithelia. Uncoordinated altered motion immotility may result subfertility even infertility. Here, we summarize current knowledge regarding localization function MCCs human discuss how beating-generated fluid flow directly indirectly contribute to processes these organs, lack improper functioning influence fertility.

Язык: Английский

Процитировано

1