rbfox1loss of function in zebrafish leads to dysregulation inbdnf/trkb2andpac1aexpression resulting in HPI axis hyperactivation, altered stress response and allostatic overload DOI Creative Commons
Adele Leggieri, Judit García‐González,

Saeedeh Hosseinian

и другие.

bioRxiv (Cold Spring Harbor Laboratory), Год журнала: 2024, Номер unknown

Опубликована: Окт. 11, 2024

ABSTRACT RBFOX1 regulates transcriptional networks linked to synaptic transmission and neurodevelopment. Mutations in the gene are associated with psychiatric disorders but how influences disorder vulnerability remains unclear. Recent studies showed that mediates alternative splicing of PAC1 , a critical HPA axis activator. Further, dysfunction is dysregulation BDNF/TrkB, pathway promoting neuroplasticity, neuronal survival, stress resilience. Hence, may increase via dysregulation, leading disrupted development allostatic overload. To test this hypothesis, we generated zebrafish rbfox1 loss function (LoF) line examined behavioural molecular effects during development. In larvae adults, LoF resulted hyperactivity, impulsivity hyperarousal, alterations proliferation, fertility traits larvae, expression pac1a, bdnf, trkb2 HPI genes. These latter were restored after chronic TrkB agonist/antagonist treatment. bdnf / axes was only seen following acute stress. Our findings revealed strict interplay between BDNF/TrkB resilience suggest predisposes diseases through hyperactivation development, impairing adaptation heightening

Язык: Английский

Evolutionary neurogenomics: Lengthy resolutions for complex brains DOI
Leonid L. Moroz

Current Biology, Год журнала: 2024, Номер 34(8), С. R315 - R318

Опубликована: Апрель 1, 2024

Язык: Английский

Процитировано

1

Decreased Brain Serotonin in rbfox1 Mutant Zebrafish and Partial Reversion of Behavioural Alterations by the SSRI Fluoxetine DOI Creative Commons

Maja R. Adel,

Ester Antón-Galindo, Edurne Gago-García

и другие.

Pharmaceuticals, Год журнала: 2024, Номер 17(2), С. 254 - 254

Опубликована: Фев. 16, 2024

RBFOX1 functions as a master regulator of thousands genes, exerting pleiotropic effect on numerous neurodevelopmental and psychiatric disorders. A potential mechanism by which may impact these disorders is through its modulation serotonergic neurotransmission, common target for pharmacological intervention in conditions linked to RBFOX1. However, the precise effects system remain largely unexplored. Here we show that homozygous rbfox1sa15940 zebrafish, express shorter, aberrant rbfox1 mRNA, have significantly reduced serotonin levels telencephalon diencephalon. We observed acute administration fluoxetine partially reverses associated behavioural alterations. The hyperactive phenotype altered shoaling behaviour rbfox1sa15940/sa15940 zebrafish could be reversed with exposure Open Field Shoaling test, respectively. other paradigms, hyperactivity was not diminished, suggesting distinct intrinsic motivation locomotion different paradigms. Acute did reverse alterations aggression social novelty tests, involvement neurological mechanisms behaviours. These findings underscore importance investigating intricate working gain better understanding along their treatment.

Язык: Английский

Процитировано

0

Identification of gene co-expression modules from zebrafish brain data: Applications in psychiatry illustrated through alcohol-related traits DOI
Laila Al‐Soufi,

Álvaro J. Arana,

Fernando Facal

и другие.

Progress in Neuro-Psychopharmacology and Biological Psychiatry, Год журнала: 2024, Номер 135, С. 111136 - 111136

Опубликована: Сен. 3, 2024

Язык: Английский

Процитировано

0

rbfox1loss of function in zebrafish leads to dysregulation inbdnf/trkb2andpac1aexpression resulting in HPI axis hyperactivation, altered stress response and allostatic overload DOI Creative Commons
Adele Leggieri, Judit García‐González,

Saeedeh Hosseinian

и другие.

bioRxiv (Cold Spring Harbor Laboratory), Год журнала: 2024, Номер unknown

Опубликована: Окт. 11, 2024

ABSTRACT RBFOX1 regulates transcriptional networks linked to synaptic transmission and neurodevelopment. Mutations in the gene are associated with psychiatric disorders but how influences disorder vulnerability remains unclear. Recent studies showed that mediates alternative splicing of PAC1 , a critical HPA axis activator. Further, dysfunction is dysregulation BDNF/TrkB, pathway promoting neuroplasticity, neuronal survival, stress resilience. Hence, may increase via dysregulation, leading disrupted development allostatic overload. To test this hypothesis, we generated zebrafish rbfox1 loss function (LoF) line examined behavioural molecular effects during development. In larvae adults, LoF resulted hyperactivity, impulsivity hyperarousal, alterations proliferation, fertility traits larvae, expression pac1a, bdnf, trkb2 HPI genes. These latter were restored after chronic TrkB agonist/antagonist treatment. bdnf / axes was only seen following acute stress. Our findings revealed strict interplay between BDNF/TrkB resilience suggest predisposes diseases through hyperactivation development, impairing adaptation heightening

Язык: Английский

Процитировано

0