Maturation of type I and type II rat vestibular hair cells in vivo and in vitro DOI Creative Commons
Mireia Borrajo, David Sedano, Aïda Palou

et al.

Frontiers in Cell and Developmental Biology, Journal Year: 2024, Volume and Issue: 12

Published: June 4, 2024

Vestibular sensory epithelia contain type I and II hair cells (HCI HCII). Recent studies have revealed molecular markers for the identification of these cells, but precise composition each vestibular epithelium (saccule, utricle, lateral crista, anterior posterior crista) their postnatal maturation not been described in detail. Moreover, vitro methods to study this are well developed. We obtained total HCI HCII counts adult rats studied from birth (P0) day 28 (P28). Adult were found comprise ∼65% expressing osteopontin PMCA2, ∼30% calretinin, ∼4% SOX2 neither nor calretinin. At birth, immature HCs express both P28 showed an almost adult-like still contained 1.3% HCs. In addition, we free-floating 3D cultures at P1, which formed a fluid-filled cyst, survival up (28 DIV). These good HC resiliency maturation. Using enriched medium initial 4 days, HCI/calretinin+-HCII ratio close vivo was obtained. suitable mature pharmacological, toxicological research.

Language: Английский

Inner Ear Organoids: Strengths and Limitations DOI Creative Commons
Giulia Pianigiani, Marta Roccio

Journal of the Association for Research in Otolaryngology, Journal Year: 2024, Volume and Issue: 25(1), P. 5 - 11

Published: Feb. 9, 2024

Abstract Inner ear organoids derived from differentiation of human pluripotent stem cells have recently gained momentum as tools to study inner development and developmental defects. An additional exciting aspect about this technology is represented by its translational potential, specifically, the use validate therapeutics for hearing balance restoration on human/patient-specific cells. This latter will be briefly discussed here including opportunities current limitations.

Language: Английский

Citations

4

Cochlear Implantation Outcomes in Genotyped Subjects with Sensorineural Hearing Loss DOI Creative Commons
M. L. A. Fehrmann, Lonneke Haer‐Wigman, Hannie Kremer

et al.

Journal of the Association for Research in Otolaryngology, Journal Year: 2025, Volume and Issue: unknown

Published: April 23, 2025

Abstract Purpose Cochlear implants (CIs) are an effective rehabilitation option for individuals with severe-to-profound sensorineural hearing loss (SNHL). While genetic factors play a significant role in SNHL, the variability CI outcomes remains unclear. This study evaluated short- and long-term large genotyped cohort investigated correlations defects their cochlear site-of-lesion. Methods retrospective, single-center, included 220 subjects (127 females; 299 ears) pathogenic variants identified 31 different nuclear genes mitochondrial genes. Audiological were measured pre- post-implantation. site-of-lesion was categorized as pre-synaptic, post-synaptic, or mitochondrial, based on gene function expression. Multiple regression analysis assessed influencing outcomes, including age at implantation, SNHL duration, aid (HA) use, Results showed median phoneme score of 90%, better early implantation (≤ 6 years). Variability not linked to site-of-lesion, but subject-specific factors, such duration pre-implantation HA experience. A model incorporating these explained 19% total variance outcomes. Poorer (phoneme scores < 70%) more common prolonged auditory deprivation older implantation. Conclusion Genotyped recipients demonstrated excellent largely attributed non-genetic factors. These findings show that is beneficial type most hereditary underscore importance

Language: Английский

Citations

0

Maturation of type I and type II rat vestibular hair cells in vivo and in vitro DOI Creative Commons
Mireia Borrajo, David Sedano, Aïda Palou

et al.

Frontiers in Cell and Developmental Biology, Journal Year: 2024, Volume and Issue: 12

Published: June 4, 2024

Vestibular sensory epithelia contain type I and II hair cells (HCI HCII). Recent studies have revealed molecular markers for the identification of these cells, but precise composition each vestibular epithelium (saccule, utricle, lateral crista, anterior posterior crista) their postnatal maturation not been described in detail. Moreover, vitro methods to study this are well developed. We obtained total HCI HCII counts adult rats studied from birth (P0) day 28 (P28). Adult were found comprise ∼65% expressing osteopontin PMCA2, ∼30% calretinin, ∼4% SOX2 neither nor calretinin. At birth, immature HCs express both P28 showed an almost adult-like still contained 1.3% HCs. In addition, we free-floating 3D cultures at P1, which formed a fluid-filled cyst, survival up (28 DIV). These good HC resiliency maturation. Using enriched medium initial 4 days, HCI/calretinin+-HCII ratio close vivo was obtained. suitable mature pharmacological, toxicological research.

Language: Английский

Citations

0